Academy of Medical Sciences of I.R. Iran Archives of Iranian Medicine 1029-2977 21 3 2018 03 01 Recurrent Pilonidal Sinus Cyst on Penis 131 133 EN Hakan Ercil Ergun Alma Mehmet Eflatun Deniz Umut Unal Alper Sozutek Journal Article 2017 01 22 2017 12 30 Pilonidal sinus, including one or more sinus canals and hairs, is a disease with a chronic course showing acute attacks which is often encountered in the general population, usually affecting young adults, at a rate in males twice that of females. Pilonidal sinus on the penis is so rare that very few cases have been reported in literature. A 20-year-old male presented to the urology outpatient clinic with the complaint of a suppurative lesion with discharge on the skin of the penis which had been ongoing for approximately three months. Clinical examination revealed an indurated, erythematous, ulcerative lesion, 3 cm x 2 cm in size, in the middle of the ventral aspect of the penile shaft. We present the first case in literature of recurrent pilonidal sinus related to Actinomyces israelii, located on the penis.