Logo-aim
Arch Iran Med. 2023;26(2): 86-91.
doi: 10.34172/aim.2023.14
PMID: 37543928
PMCID: PMC10685898
Scopus ID: 85164787469
  Abstract View: 976
  PDF Download: 659

Original Article

A Form of Metabolic-Associated Fatty Liver Disease Associated with a Novel LIPA Variant

Amir Anushiravani 1 ORCID logo, Hossein Jafari Khamirani 2 ORCID logo, Ashraf Mohamadkhani 1, Arya Mani 3,4, Mehdi Dianatpour 2,5* ORCID logo, Reza Malekzadeh 1* ORCID logo

1 Digestive Diseases Research Institute, Tehran University of Medical Sciences, Tehran, Iran
2 Department of Medical Genetics, Shiraz University of Medical Sciences, Shiraz, Iran
3 Cardiovascular Research Center, Department of Internal Medicine, Yale University School of Medicine, New Haven, Connecticut, USA
4 Department of Genetics, Yale University School of Medicine, New Haven, Connecticut, USA
5 Stem Cells Technology Research Center, Shiraz University of Medical Sciences, Shiraz, Iran
*Corresponding Authors: Mehdi Dianatpour, Email: mdianatpur@gmail.com; Reza Malekzadeh, Email: malek@tums.ac.ir

Abstract

Background: The LIPA gene on chromosome 10q23.31 contains 10 exons and encodes lipase A, the lysosomal acid lipase (LAL) containing 399 amino acids. Pathogenic variants in the LIPA result in autosomal recessive Wolman disease and cholesteryl ester storage disease (CESD). Here, we report a novel missense variant (NM_001127605.3:c.928T>A, p.Trp310Arg) of LIPA in an Iranian family with fatty liver disease identified by whole-exome sequencing and confirmed by Sanger sequencing.

Methods: A 28-year-old woman referred with lean NASH cirrhosis and extremely high cholesterol levels. Fatty liver disease was found in six of her family members using vibration-controlled transient elastography (VCTE). Baseline routine laboratory tests were performed and whole-exome sequencing and confirmation by Sanger sequencing were done.

Results: The index case had severe dyslipidemia and cirrhosis despite a body mass index of 21.09 kg/m2 . Six other family members had dyslipidemia and fatty liver or cirrhosis. A homozygous missense variant (NM_001127605.3:c.928T>A, p.Trp310Arg) of LIPA which caused LAL-D was found to be associated with fatty liver disease and/or cirrhosis.

Conclusion: A homozygous missense variant (NM_001127605.3:c.928T>A, p.Trp310Arg) of the LIPA gene which caused LAL-D was found to be associated with dyslipidemia, fatty liver disease and/or cirrhosis in six members of an Iranian family. These results should be confirmed by functional studies and extending the study to at least three families.


Cite this article as: Anushiravani A, Jafari Khamirani H, Mohamadkhani A, Mani A, Dianatpour M, Malekzadeh R. A form of metabolic-associated fatty liver disease associated with a novel LIPA variant. Arch Iran Med. 2023;26(2):86-91. doi: 10.34172/ aim.2023.14
First Name
Last Name
Email Address
Comments
Security code


Abstract View: 977

Your browser does not support the canvas element.


PDF Download: 659

Your browser does not support the canvas element.

Submitted: 15 Nov 2022
Accepted: 16 Nov 2022
ePublished: 01 Feb 2023
EndNote EndNote

(Enw Format - Win & Mac)

BibTeX BibTeX

(Bib Format - Win & Mac)

Bookends Bookends

(Ris Format - Mac only)

EasyBib EasyBib

(Ris Format - Win & Mac)

Medlars Medlars

(Txt Format - Win & Mac)

Mendeley Web Mendeley Web
Mendeley Mendeley

(Ris Format - Win & Mac)

Papers Papers

(Ris Format - Win & Mac)

ProCite ProCite

(Ris Format - Win & Mac)

Reference Manager Reference Manager

(Ris Format - Win only)

Refworks Refworks

(Refworks Format - Win & Mac)

Zotero Zotero

(Ris Format - Firefox Plugin)